The New England Journal of Medicine OCTOBER 31, 2019

Nintedanib in Progressive Fibrosing Interstitial Lung Diseases

Kevin R. Flaherty, Athol U. Wells, Vincent Cottin, et al. for the INBUILD Trial Investigators

Bottom Line

The INBUILD trial demonstrated that nintedanib reduces the rate of lung function decline in patients with progressive fibrosing interstitial lung diseases (ILDs) other than idiopathic pulmonary fibrosis.

Key Findings

1. Over the trial period, nintedanib reduced the risk of ILD progression (defined as an absolute decline in forced vital capacity (FVC) ≥10% predicted) or death by 34% compared to placebo (hazard ratio (HR) 0.66; 95% CI 0.53–0.83; p=0.0003).
2. In the subgroup of patients with a usual interstitial pneumonia (UIP)-like fibrotic pattern on HRCT, nintedanib reduced the risk of ILD progression or death by 31% (HR 0.69; 95% CI 0.53–0.91; p=0.009).
3. Nintedanib also reduced the risk of acute ILD exacerbation or death by 33% in the overall population (HR 0.67; 95% CI 0.46–0.98; p=0.04).
4. The most frequent adverse event associated with nintedanib was diarrhea, occurring in approximately 67% of the treated population compared to 24% in the placebo group.

Study Design

Design
RCT
Double-Blind
Sample
663
Patients
Duration
15.6 mo
Median
Setting
Multicenter, international
Population Adults with fibrosing ILDs other than idiopathic pulmonary fibrosis who exhibited disease progression within the previous 24 months despite standard management.
Intervention Nintedanib 150 mg twice daily
Comparator Placebo twice daily
Outcome Annual rate of decline in forced vital capacity (FVC) measured in mL over 52 weeks.

Study Limitations

The trial included a diverse array of ILD diagnoses, which may limit the generalizability of results to specific, individual ILD etiologies.
The study was not specifically powered to demonstrate efficacy within individual diagnostic subgroups.
The observed reduction in functional decline did not translate into a statistically significant improvement in quality of life metrics (e.g., K-BILD scores).
Gastrointestinal side effects were common, which may pose challenges for long-term adherence in clinical practice.

Clinical Significance

The INBUILD trial established a standardized, evidence-based treatment option for a broad range of non-IPF progressive fibrosing ILDs, shifting the paradigm from disease-specific management to a phenotype-driven treatment approach.

Historical Context

Prior to the INBUILD trial, nintedanib was approved solely for the treatment of idiopathic pulmonary fibrosis (IPF) and systemic sclerosis-associated ILD (SSc-ILD). This trial addressed the significant unmet clinical need for patients with various fibrosing lung diseases that exhibit a progressive phenotype regardless of their specific etiology.

Guided Discussion

High-yield insights from every perspective

Med Student
Medical Student

How does the molecular mechanism of nintedanib's tyrosine kinase inhibition specifically target the pathophysiology of progressive fibrosis across diverse interstitial lung diseases?

Key Response

Nintedanib inhibits multiple tyrosine kinases, including Vascular Endothelial Growth Factor Receptor (VEGFR), Platelet-Derived Growth Factor Receptor (PDGFR), and Fibroblast Growth Factor Receptor (FGFR). These receptors drive the activation, proliferation, and migration of fibroblasts and their transformation into myofibroblasts. This 'final common pathway' of fibrogenesis occurs regardless of the initial trigger, explaining why the drug is effective in various ILDs like hypersensitivity pneumonitis and autoimmune-related ILD.

Resident
Resident

Based on the inclusion criteria of the INBUILD trial, what specific clinical parameters define 'progressive' fibrosing ILD for a patient who does not have Idiopathic Pulmonary Fibrosis (IPF)?

Key Response

Progression was defined as meeting at least one of the following criteria within the previous 24 months despite conventional management: a decline in Forced Vital Capacity (FVC) of at least 10% predicted; a decline in FVC of 5-10% predicted combined with worsening respiratory symptoms or increased fibrosis on HRCT; or worsening symptoms and increased extent of fibrotic abnormality on HRCT.

Fellow
Fellow

How should the presence of a Usual Interstitial Pneumonia (UIP)-like pattern on high-resolution CT (HRCT) influence your interpretation of nintedanib's efficacy in non-IPF progressive fibrosing ILDs?

Key Response

In the INBUILD trial, while nintedanib significantly reduced the rate of FVC decline in the overall population, the effect size was numerically larger in patients with a UIP-like fibrotic pattern (-82.9 mL/yr vs -211.1 mL/yr in placebo) compared to those with other fibrotic patterns (-79.0 mL/yr vs -159.2 mL/yr in placebo). This suggests that a UIP-like morphology may indicate a faster-progressing disease state that is highly responsive to antifibrotic therapy.

Attending
Attending

How does the INBUILD data shift our clinical paradigm from an etiology-based diagnostic approach to a phenotype-based management strategy in interstitial lung disease?

Key Response

The trial demonstrates that once a patient develops a 'progressive fibrosing phenotype,' the underlying biological process of lung destruction becomes somewhat independent of the initial cause (e.g., rheumatoid arthritis or sarcoidosis). This shifts the focus from solely treating the primary inflammatory/autoimmune driver to adding antifibrotic therapy once progression is documented, creating a new therapeutic category known as Progressive Pulmonary Fibrosis (PPF).

Scholarly Review

Critical appraisal through the lens of expert reviewers and guideline development

PhD
PhD

The INBUILD trial utilized a 'basket trial' design to evaluate nintedanib across various ILD diagnoses. What are the statistical risks associated with this design regarding the generalizability of findings to rare individual ILD subtypes included in the cohort?

Key Response

The primary risk is 'heterogeneity of treatment effect' across the different underlying etiologies (e.g., iNSIP vs. chronic HP). Because the trial was powered for the aggregate group and the UIP-like subgroup, it lacks the power to confirm if every specific subtype benefits equally. A PhD would argue that while the biological rationale for a shared pathway is strong, the statistical evidence for any one rare ILD within the 'basket' remains indirect.

Journal Editor
Journal Editor

What are the primary threats to the internal validity of the INBUILD trial regarding the maintenance of the blind, given the known adverse effect profile of nintedanib?

Key Response

Nintedanib is strongly associated with gastrointestinal side effects, specifically diarrhea (reported in 66.9% of the nintedanib group vs 23.9% of placebo). A seasoned reviewer would flag that this high rate of a recognizable adverse event could lead to 'unblinding' by both patients and investigators, potentially influencing the reporting of subjective secondary outcomes like quality-of-life scores or symptom worsening.

Guideline Committee
Guideline Committee

Given the 2022 ATS/ERS/JRS/ALAT clinical practice guideline on Progressive Pulmonary Fibrosis (PPF), where does nintedanib fit in the hierarchy of recommendations compared to its role in IPF?

Key Response

The 2022 guidelines provide a 'conditional recommendation' for nintedanib in PPF based on 'low quality of evidence' for specific outcomes like mortality, whereas in IPF, the recommendation is more established. Guidelines suggest nintedanib for patients who show evidence of progression despite 'standard' therapy (like immunosuppression in connective tissue disease-ILD), effectively positioning it as a key second-line or combination therapy rather than an immediate first-line replacement for steroids/DMARDs.

Clinical Landscape

Noteworthy Related Trials

2010

CAPACITY Trials

n = 779 · Lancet

Tested

Pirfenidone

Population

Patients with idiopathic pulmonary fibrosis

Comparator

Placebo

Endpoint

Change in percent predicted forced vital capacity at week 72

Key result: One of the two trials met its primary endpoint, demonstrating that pirfenidone reduced the decline in lung function.
2012

PANTHER-IPF Trial

n = 341 · NEJM

Tested

Prednisone, azathioprine, and N-acetylcysteine

Population

Patients with idiopathic pulmonary fibrosis

Comparator

Placebo

Endpoint

Death or hospitalization

Key result: The combination therapy was associated with an increased risk of death and hospitalization compared to placebo.
2014

ASCEND Trial

n = 555 · NEJM

Tested

Pirfenidone 2403 mg daily

Population

Patients with idiopathic pulmonary fibrosis

Comparator

Placebo

Endpoint

Change in percent predicted forced vital capacity (FVC)

Key result: Pirfenidone significantly reduced the decline in FVC compared to placebo over 52 weeks.

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