Circulation NOVEMBER 18, 2024

Mavacamten in Patients With Hypertrophic Cardiomyopathy Referred for Septal Reduction: Week 128 Results From VALOR-HCM

Milind Y. Desai, et al.

Bottom Line

The VALOR-HCM trial demonstrates that long-term mavacamten therapy in severely symptomatic patients with obstructive hypertrophic cardiomyopathy who are eligible for septal reduction therapy (SRT) results in sustained reductions in the need for invasive SRT, alongside persistent improvements in NYHA class and left ventricular outflow tract gradients.

Key Findings

1. At week 128, only 15.7% (17 of 108) of patients met the primary composite endpoint of having undergone SRT or remaining guideline-eligible for SRT.
2. A substantial proportion of patients experienced symptomatic benefit, with 80.5% (87 of 108) achieving a New York Heart Association (NYHA) class improvement of ≥1, and 48.1% (52 of 108) achieving an improvement of ≥2.
3. Cardiac hemodynamics showed significant and sustained improvement, with resting and Valsalva left ventricular outflow tract gradients reduced by 38.2 mm Hg and 59.4 mm Hg, respectively.
4. Long-term treatment was generally well-tolerated, with 88% (95 of 108) of participants opting to transition to commercial mavacamten upon trial completion.
5. Safety monitoring revealed that 13.8% (15 of 108) of patients experienced a left ventricular ejection fraction (LVEF) <50% during the study, although 80% of these individuals were able to continue mavacamten therapy.

Study Design

Design
RCT
Double-Blind
Sample
108
Patients
Duration
128 wk
Median
Setting
Multicenter, US
Population Adults with symptomatic (NYHA Class III-IV or Class II with syncope) obstructive hypertrophic cardiomyopathy currently eligible for and referred for septal reduction therapy.
Intervention Mavacamten (titrated to maintain LVEF and reduce LVOT gradients).
Comparator Placebo (with cross-over to mavacamten at week 16).
Outcome Composite of the proportion of patients proceeding with septal reduction therapy or remaining guideline-eligible for septal reduction therapy at week 128.

Study Limitations

The study design included a crossover component for the placebo arm, which complicates the long-term comparison of absolute treatment effects against a control group after week 16.
A small proportion (nine patients) had unevaluable SRT status at the end of the trial, which were conservatively counted as meeting the primary endpoint of treatment failure.
The trial was conducted exclusively in the United States, which may impact the generalizability of results to other healthcare systems with different referral patterns or access to SRT.
While mavacamten effectively reduced the need for SRT, it requires rigorous longitudinal echocardiographic monitoring due to the risk of reversible LVEF reduction.

Clinical Significance

VALOR-HCM provides high-quality evidence that mavacamten is an effective, non-invasive pharmacological alternative for highly symptomatic patients with obstructive hypertrophic cardiomyopathy who have been referred for invasive septal reduction therapy, potentially allowing them to avoid or delay surgery or alcohol septal ablation.

Historical Context

Historically, management for patients with symptomatic obstructive HCM refractory to standard medical therapies (such as beta-blockers and calcium channel blockers) was largely limited to invasive septal reduction therapies (myectomy or alcohol ablation). Mavacamten, a first-in-class cardiac myosin inhibitor, represents a paradigm shift in HCM treatment by directly targeting the underlying molecular pathophysiology of hypercontractility.

Guided Discussion

High-yield insights from every perspective

Med Student
Medical Student

What is the primary molecular mechanism of mavacamten, and how does it specifically target the pathophysiology of obstructive hypertrophic cardiomyopathy (oHCM)?

Key Response

Mavacamten is a first-in-class selective cardiac myosin inhibitor. It works by binding to cardiac myosin and shifting it into a 'super-relaxed' state, which reduces the number of myosin-actin cross-bridges that can form. In oHCM, there is an excess of these cross-bridges leading to hypercontractility and impaired relaxation; mavacamten normalizes this, thereby reducing the left ventricular outflow tract (LVOT) gradient and improving diastolic filling.

Resident
Resident

In a patient with oHCM who remains symptomatic despite maximally tolerated beta-blocker therapy, how do the results of the VALOR-HCM 128-week study change the management algorithm regarding septal reduction therapy (SRT)?

Key Response

The 128-week data from VALOR-HCM demonstrates that mavacamten can serve as a highly effective medical alternative to invasive SRT (myectomy or alcohol septal ablation). The study showed that the majority of patients who were previously eligible for SRT no longer met the clinical or hemodynamic criteria for the procedure after long-term mavacamten use, effectively allowing patients to avoid or significantly delay surgery while maintaining symptomatic improvement (NYHA class reduction).

Fellow
Fellow

The VALOR-HCM long-term extension reported that a small percentage of patients experienced a transient drop in left ventricular ejection fraction (LVEF) to <50%. How should this affect the clinical monitoring strategy for a patient on long-term cardiac myosin inhibitor therapy?

Key Response

Fellows must recognize the necessity of the REMS (Risk Evaluation and Mitigation Strategy) program. The 128-week data confirms that while LVEF reductions are generally reversible upon dose interruption or adjustment, they occur even in long-term stable patients. This necessitates continued, periodic echocardiographic monitoring of LVEF and LVOT gradients to ensure safety, as the drug’s potent effect on contractility carries a risk of inducing iatrogenic systolic heart failure.

Attending
Attending

Considering the 128-week results of VALOR-HCM, how would you counsel a 45-year-old symptomatic oHCM patient choosing between surgical myectomy and long-term mavacamten therapy?

Key Response

The counseling must pivot to a 'shared decision-making' model comparing the 'one-and-done' nature of surgical myectomy (which has decades of proven durability and may eliminate the need for daily specialized medications) versus the chronic medical management with mavacamten. While VALOR-HCM shows sustained benefit over 2.5 years, we still lack 10-20 year data on mavacamten, making the choice a balance between avoiding the immediate risks of open-heart surgery and the unknown long-term implications of chronic myosin inhibition.

Scholarly Review

Critical appraisal through the lens of expert reviewers and guideline development

PhD
PhD

Critique the use of 'eligibility for septal reduction therapy' as a primary endpoint in the VALOR-HCM trial; what are the methodological strengths and weaknesses of using a guideline-based procedural recommendation as a proxy for clinical status?

Key Response

The strength lies in its clinical relevance, as it directly addresses a major milestone in the patient's disease trajectory (avoidance of surgery). However, the weakness is the inherent subjectivity of the 'referral' process and the potential for 'unblinding' in an open-label extension. If both the investigator and patient are aware of the treatment and the patient feels better, there is a strong bias against proceeding with surgery even if hemodynamic criteria are marginally met, which can inflate the perceived success of the drug in avoiding SRT.

Journal Editor
Journal Editor

As a reviewer, what concerns would you raise regarding the 'survivor bias' or attrition in the 128-week results of the VALOR-HCM study, and how might this affect the generalizability of the findings?

Key Response

A critical reviewer would note that patients who do not tolerate mavacamten or do not see early benefit are more likely to drop out of the long-term extension to pursue SRT or other treatments. Therefore, the 128-week results likely represent a 'best-case scenario' involving patients who are both responders and tolerant of the medication. The reported 90%+ avoidance of SRT may not apply to the entire initial intention-to-treat population if the attrition rate and reasons for discontinuation are not rigorously accounted for.

Guideline Committee
Guideline Committee

Based on the VALOR-HCM 128-week data, should mavacamten be recommended as a first-line therapy for symptomatic oHCM, and how does this evidence compare to the current Class 2a recommendation in the 2024 AHA/ACC guidelines?

Key Response

Currently, the 2024 AHA/ACC HCM guidelines recommend cardiac myosin inhibitors (Class 2a) for patients with persistent symptoms despite first-line agents (beta-blockers/calcium channel blockers). The VALOR-HCM data provides the level of evidence regarding 'durability' that might move the needle toward a Class 1 recommendation. However, the committee must consider that SRT still holds a Class 1 recommendation for refractory symptoms due to its historical success; mavacamten is currently positioned as an alternative to SRT, but not yet as a replacement for traditional first-line medical therapy (beta-blockers).

Clinical Landscape

Noteworthy Related Trials

2018

PIONEER-HCM Trial

n = 21 · JACC

Tested

Mavacamten

Population

Symptomatic obstructive hypertrophic cardiomyopathy

Comparator

Placebo

Endpoint

Change in resting and post-exercise LVOT gradient

Key result: Mavacamten therapy resulted in a significant reduction of LVOT gradients and improvement in symptoms in patients with obstructive HCM.
2020

EXPLORER-HCM Trial

n = 251 · Lancet

Tested

Mavacamten

Population

Symptomatic obstructive hypertrophic cardiomyopathy

Comparator

Placebo

Endpoint

Composite of change in pVO2 and NYHA functional class

Key result: Mavacamten significantly improved exercise capacity and symptoms in patients with obstructive HCM.
2023

VALOR-HCM Primary Analysis

n = 112 · JACC

Tested

Mavacamten

Population

Obstructive HCM patients eligible for septal reduction therapy

Comparator

Placebo

Endpoint

Decision to proceed with septal reduction therapy or continued eligibility at week 16

Key result: Mavacamten significantly reduced the need for septal reduction therapy compared to placebo in eligible patients.

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